The SMPDL3B-Shedding Phenotype

A Feedback-Loop Architecture Explaining Persistence, Oscillation, and Relapse in ME/CFS

Author: Michael Daniels · Version 2.4 · December 2025

Myalgic encephalomyelitis / chronic fatigue syndrome (ME/CFS) is characterized by exertion intolerance, delayed post-exertional malaise (PEM), autonomic instability, and fluctuating vascular and metabolic abnormalities that often evade detection by resting clinical tests.

Existing models have described immune activation, endothelial dysfunction, autonomic dysregulation, and metabolic impairment, but frequently struggle to explain three persistent clinical features: (1) why symptoms worsen after exertion rather than during it, (2) why physiological function can appear near-normal at rest yet collapse under load, and (3) why partial recovery fails to restore prior resilience, leading to relapse and threshold erosion over time.

This document proposes a systems-level feedback architecture intended to address these gaps.

Core Thesis

The SMPDL3B-shedding phenotype represents a state-dependent, membrane-gated instability within the Gut–Liver–Autonomic (GLA) axis in myalgic encephalomyelitis / chronic fatigue syndrome (ME/CFS) and related post-infectious conditions.

Rather than arising from fixed structural damage or continuous immune activation, disease persistence in this phenotype is maintained by episodic SMPDL3B cleavage, ion and calcium stress, and recovery-phase vulnerability, which together lower activation thresholds across immune, vascular, autonomic, and metabolic systems.

Critically, SMPDL3B expression is not permanently suppressed. Partial recovery between episodes occurs, but is incomplete, allowing each stressor to leave residual instability that increases susceptibility to future decompensation.

This architecture explains three otherwise puzzling clinical features:
  • why post-exertional malaise (PEM) is delayed rather than immediate
  • why perfusion and autonomic failure are brittle and load-dependent, not continuously abnormal
  • why partial recovery between episodes does not restore prior resilience, leading to relapse and threshold erosion over time

Central claim: not that SMPDL3B loss causes ME/CFS, but that state-dependent, load-dependent SMPDL3B shedding functions as a gate that converts otherwise tolerable physiological stress into multi-system failure when specific thresholds are crossed.

Artifact status (v2.4): This document’s structure, figure numbering, and terminology are locked (canonical) for submission and citation. Mechanistic links remain provisional / hypothesis-level and are presented for systems reasoning and testable prediction.
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How to Read This Architecture

This document explains why the system fails to reset, not where the illness begins. It specifies the closed feedback interactions that sustain instability, produce oscillation, and drive relapse in the SMPDL3B-shedding phenotype.

The shedding phenotype is best understood as an oscillatory system:

  • primed at baseline
  • destabilized during stress
  • most vulnerable during recovery
  • partially restored between episodes, but never fully reset

To make this persistence logic explicit, the feedback loops underlying the SMPDL3B-shedding phenotype are organized into four interacting layers, progressing from root cellular stress to relapse architecture.

Relationship to companion documents
This architecture is intended to be read alongside the following related works:

GLA v2.1 — Gut–Liver–Autonomic Axis (Foundational Framework)
Provides the systems-level context in which the mechanisms discussed here operate, including vascular, autonomic, hepatic, and metabolic regulation.

GLA v2.3 — Core Framework Addition
Extends the GLA framework with EV-glycome biology, ER–Golgi stress, hepatic load, and SMPDL3B-centered membrane instability, establishing the upstream constraints that shape the feedback-loop behavior described in this document.

SMPDL3B-Shedding Systems Framework v2.4
Defines what biological mechanisms are involved and where instability emerges using a linear mechanistic specification. The present document explains why those mechanisms fail to fully reset, producing persistence, oscillation, and relapse.

How to interpret “loops” in this document
The loops described here are not linear steps or a temporal sequence. They represent closed feedback structures that can remain latent, become partially engaged, or dominate system behavior depending on state.

Key interpretive principles:

  • Loops describe persistence logic, not disease initiation
  • Engagement is state-dependent and load-sensitive
  • Loops may weaken or disengage with sufficient recovery
  • Not all loops are active in all patients or at all times
  • This architecture is phenotype-specific (shedding ≠ deficient)

This document should therefore be read as a systems persistence map, not a diagnostic tool or treatment protocol. Mechanisms remain hypothesis-level and are intended to be evaluated, refined, or falsified as evidence advances.


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The Four-Layer Feedback Architecture

Figure 1 — Feedback loop architecture of the SMPDL3B-shedding phenotype Four-layer architecture from priming → shedding execution → functional perfusion failure → recovery-phase relapse (delayed PEM) Layer 1 Layer 2 Layer 3 Layer 4 Membrane & Cellular Stress ER–Golgi stress + altered EV glycosylation Primed baseline (trigger-ready without continuous activation) lowered thresholds fluctuating biomarkers Ion, Innate, and Proteolytic Amplification PI-PLC–linked GPI-anchor cleavage → episodic SMPDL3B shedding Lipid raft destabilization + Na⁺/Ca²⁺ stress + innate sensitization ROS amplification closes short, fast feedback loops Na⁺ → Ca²⁺ TLR4 sensitivity ROS threshold lowering Functional Perfusion Failure Brittle endothelial control (preserved at rest, unreliable under load) Perfusion distribution failure → regional ischemia → metabolic stress signals brittle eNOS/NO regional ischemia Recovery Failure & Relapse Architecture Peak demand in recovery: ATP buffering + ion rebalancing + membrane repair Delayed mitochondrial stress re-engages PI-PLC after stressor ends → delayed PEM delayed PEM threshold erosion stress exceeds tolerance recovery window incomplete recovery increases re-trigger probability metabolic stress feeds back forward propagation feedback persistence
Figure 1. Feedback loop architecture of the SMPDL3B-shedding phenotype in ME/CFS. The SMPDL3B-shedding phenotype is characterized by state-dependent membrane instability that lowers physiological activation thresholds across immune, vascular, autonomic, and metabolic systems. Baseline ER–Golgi stress and altered extracellular vesicle glycosylation maintain a primed but non-inflamed state. Under stress, episodic SMPDL3B shedding destabilizes membrane microdomains, producing ion dysregulation, innate sensitization, and proteolytic amplification. These events propagate downstream as brittle endothelial nitric oxide signaling and perfusion distribution failure that appear near-normal at rest but fail under demand. The dominant vulnerability occurs during the recovery phase, when delayed metabolic and ionic stress re-engages membrane instability, producing delayed post-exertional malaise (PEM) and incomplete recovery. Repeated cycles lead to threshold erosion and relapse susceptibility despite partial inter-episode recovery.
Layer 1

Membrane & Cellular Stress

(Trigger readiness without continuous activation)

At baseline, the SMPDL3B-shedding system exists in a primed but not inflamed state.

Persistent ER–Golgi stress and altered extracellular vesicle (EV) glycosylation bias innate immune signaling toward alertness rather than activation. These signals do not drive sustained cytokine elevation or suppress SMPDL3B expression transcriptionally. Instead, they maintain a cellular environment that is stress-responsive and biased toward stress-activated proteolytic permissiveness.

Crucially, this layer explains why:

  • patients may appear immunologically “quiet” at rest
  • inflammatory markers fluctuate rather than remain elevated
  • minor stressors repeatedly re-engage downstream cascades
Key insight:
Disease persistence begins with lowered activation thresholds, not constant immune activity.
Layer 2

Ion, Innate, and Proteolytic Amplification

(Episode escalation and threshold lowering)

When stress exceeds tolerance, episodic SMPDL3B shedding occurs via PI-PLC–linked GPI-anchor cleavage.

Transient loss of membrane-anchored SMPDL3B destabilizes lipid rafts, impairing tight regulation of ion channels and innate receptors. This produces:

  • intracellular sodium accumulation
  • secondary calcium dysregulation
  • stress-responsive microRNA activation
  • heightened TLR4 sensitivity through lowered activation thresholds rather than constitutive signaling

Calcium overload and mitochondrial stress generate reactive oxygen species (ROS), which feed back into ER stress, innate signaling, and protease permissiveness—closing short, fast feedback loops that rapidly amplify instability once shedding begins.

Because SMPDL3B expression is not permanently suppressed, partial recovery occurs. However, each episode leaves the system more easily destabilized during subsequent stress windows.

Key insight:
Once shedding is initiated, multiple reinforcing loops cooperate to lower future thresholds, explaining why one crash primes the next.
Layer 3

Functional Perfusion Failure

(System-level expression under demand)

Membrane and ion-level instability propagate downstream as brittle vascular control rather than fixed endothelial disease.

Endothelial nitric oxide (NO) signaling is typically preserved at rest but becomes unreliable under load due to calcium stress and oxidative uncoupling. The result is perfusion distribution failure:

  • some microvascular beds are over-perfused
  • others become ischemic
  • global blood pressure and cardiac output may remain normal - particularly under resting conditions

Regional ischemia generates metabolic stress signals that further increase calcium dysregulation, mitochondrial strain, and innate activation—feeding back into the membrane-level shedding machinery.

Autonomic compensation initially stabilizes perfusion but does so at the cost of increased sympathetic tone, calcium flux, and metabolic demand, which worsen upstream instability.

Key insight:
Vascular failure in this phenotype is functional and load-dependent, not continuously measurable at rest.
Layer 4

Recovery Failure & Relapse Architecture

(Why the system does not reset)

The defining vulnerability of the SMPDL3B-shedding phenotype emerges during the recovery phase.

After exertion or stress, demands peak simultaneously across:

  • ATP buffering
  • ion rebalancing
  • membrane repair
  • inflammatory resolution
  • metabolic clearance (including hepatic buffering)

In this window, delayed mitochondrial stress, calcium dysregulation, and oxidative signaling peak during the recovery phase, re-engaging PI-PLC activity and membrane instability after the stressor has ended, producing delayed PEM.

Because recovery is incomplete, each episode leaves residual instability:

  • membrane repair is partial
  • metabolic flexibility is reduced
  • autonomic compensation remains sensitized
  • immune resolution is incomplete

Over time, this produces threshold erosion—the characteristic shrinking envelope of tolerance and increasing relapse risk.

Key insight:
PEM is not an exertional failure but a recovery-phase failure, maintained by interacting feedback loops rather than irreversible damage.
Synthesis

Why This Matters

This architecture explains how ME/CFS in the SMPDL3B-shedding phenotype can:

  • persist without continuous inflammation
  • relapse without new infection
  • worsen despite partial recovery
  • evade detection by resting tests
  • respond paradoxically to mistimed interventions

It also implies that preventing small crashes, stabilizing recovery windows, and respecting phase-dependent vulnerability may be as important as targeting any single downstream pathway.

One-Sentence Summary
The SMPDL3B-shedding phenotype is best understood as a membrane-gated, recovery-limited systems disorder, in which delayed PEM and relapse emerge from interacting feedback loops that lower physiological thresholds over time rather than from fixed structural damage.
Layer 1 ER–Golgi stress EV glycome priming threshold lowering Layer 2 PI-PLC shedding Na⁺ → Ca²⁺ stress ROS amplification Layer 3 brittle eNOS perfusion mismatch regional ischemia Layer 4 recovery overload delayed PEM threshold erosion Closed-loop persistence: partial recovery without full reset → rising re-trigger probability
Mini-schematic: Four-layer feedback architecture from priming to recovery-phase relapse.

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Feedback Loop Families in the SMPDL3B-Shedding Phenotype

This section groups the canonical feedback loops underlying the SMPDL3B-shedding phenotype into five functional families, each answering a specific systems-level question about disease persistence, oscillation, and relapse.

Rather than replacing the formal loop definitions (Appendix A), this organization provides a conceptual scaffold that allows readers to understand how multiple reinforcing loops cooperate across biological scales.

Loop Family I

Priming & Trigger Readiness

(Canonical Loops 1–2)

Systems question addressed:
Why does the system remain persistently trigger-ready without continuous inflammation or fixed dysfunction?

Core dynamics

The SMPDL3B-shedding phenotype is maintained in a primed baseline state by interacting cellular stress processes rather than by sustained immune activation.

ER–Golgi stress alters protein trafficking and glycan maturation, producing extracellular vesicles (EVs) enriched in high-mannose and immature N-glycan structures. These EVs function as low-grade danger signals, engaging lectin pathways and innate sensors in a contextual, non-saturating manner.

Crucially, this signaling:

  • biases innate pathways toward alertness rather than activation
  • does not chronically suppress SMPDL3B expression
  • maintains stress-responsive cellular programs
  • increases reliance on rapid membrane turnover and stress-activated proteolysis

ER–Golgi stress and altered EV signaling reinforce one another, closing a loop that keeps the system persistently susceptible to re-triggering without producing continuous inflammatory pathology.

What this family reinforces

  • Persistent immune and cellular “readiness”
  • Lowered activation thresholds across downstream pathways
  • Fluctuating biomarkers rather than sustained abnormalities
  • Apparent clinical quiescence punctuated by instability
Key insight:
The disease state is maintained by baseline priming, not ongoing activation.
Loop Family II

Shedding Execution & Threshold Lowering

(Canonical Loops 3–6)

Systems question addressed:
Why does one shedding episode make subsequent episodes easier to trigger?

Core dynamics

When physiological stress exceeds tolerance, episodic SMPDL3B shedding occurs via PI-PLC–mediated GPI-anchor cleavage.

Loss of membrane-anchored SMPDL3B transiently destabilizes lipid rafts, impairing tight regulation of:

  • ion channels
  • innate receptors
  • membrane signaling microdomains

This produces intracellular sodium accumulation with secondary calcium dysregulation, activating stress-responsive microRNA programs and sensitizing innate signaling pathways.

Calcium overload drives mitochondrial stress and ROS generation, which feed back into:

  • ER stress
  • innate signaling bias
  • PI-PLC permissiveness
  • renewed membrane instability

Because SMPDL3B transcription is preserved, membrane integrity can partially recover between episodes. However, each episode leaves residual instability, lowering the threshold for future shedding.

What this family reinforces

  • Rapid escalation once shedding begins
  • Progressive lowering of activation thresholds
  • Oscillatory instability rather than fixed dysfunction
  • Increasing crash susceptibility over time
Key insight:
Threshold erosion emerges from repeated execution-level feedback, not permanent molecular loss.
Loop Family III

Functional Perfusion Failure

(Canonical Loops 7–8; GLA v2.1 integration)

Systems question addressed:
Why does vascular failure appear normal at rest yet collapse under demand?

Core dynamics

Membrane and ion instability propagate downstream into the vascular system as brittle endothelial control, not structural vessel disease.

Calcium stress and oxidative signaling disrupt endothelial membrane platforms required for stable eNOS regulation. Nitric oxide signaling is therefore:

  • preserved or near-normal at rest
  • unreliable during physiological demand

This produces perfusion distribution failure, in which regional microvascular beds become ischemic despite preserved global hemodynamics.

Regional ischemia generates metabolic stress signals that further increase calcium dysregulation, mitochondrial ROS, and innate signaling—feeding directly back into upstream membrane instability and shedding susceptibility.

What this family reinforces

  • “Normal” resting vascular tests
  • Severe exertional or orthostatic intolerance
  • Regional hypoxia without systemic hypotension
  • Hidden ischemia driving downstream stress signaling
Key insight:
Perfusion failure in this phenotype is functional, load-dependent, and state-dependent, not fixed or continuously measurable.
Loop Family IV

Autonomic & Renal Lock-In

(Canonical Loops 9–10)

Systems question addressed:
Why do compensatory responses worsen long-term stability rather than restore it?

Core dynamics

Autonomic compensation initially stabilizes perfusion during vascular brittleness via sympathetic activation. However, sustained sympathetic tone:

  • increases intracellular calcium flux
  • raises metabolic demand
  • worsens microvascular flow heterogeneity

These changes directly amplify upstream membrane instability and PI-PLC activation, increasing the probability of renewed SMPDL3B shedding.

Simultaneously, unreliable microvascular perfusion produces state-dependent renal hypoperfusion, destabilizing sodium and water handling. Volume instability worsens orthostatic stress, further increasing sympathetic drive and closing a reinforcing loop between autonomic activation, vascular mismatch, and renal low-flow states.

What this family reinforces

  • Persistent sympathetic bias
  • Orthostatic intolerance without fixed hypotension
  • Sensitivity to dehydration, heat, and posture
  • Increasing reliance on compensatory mechanisms that amplify instability
Key insight:
Compensation becomes pathogenic when it increases demand and calcium flux in a threshold-lowered system.
Loop Family V

Recovery Failure & Relapse Architecture

(Canonical Loops 11–16)

Systems question addressed:
Why does partial recovery fail to restore resilience, producing delayed PEM and relapse?

Core dynamics

The dominant vulnerability in the SMPDL3B-shedding phenotype occurs during the recovery phase, not during exertion itself.

Following stress, simultaneous demands peak across:

  • ATP buffering
  • ion rebalancing
  • membrane repair
  • inflammatory resolution
  • metabolic clearance (including hepatic buffering)

In this window, delayed mitochondrial stress, calcium dysregulation, and oxidative signaling peak during recovery, re-engaging PI-PLC activity and membrane instability after the stressor has ended. This produces delayed PEM rather than immediate collapse.

Repeated stress episodes impose episodic hepatic metabolic load, reducing recovery depth and metabolic flexibility. Immune resolution remains incomplete between episodes, leaving the system primed for re-triggering.

Each crash leaves residual buffering loss—threshold erosion—making future crashes easier to provoke and harder to recover from.

What this family reinforces

  • Delayed PEM (12–48+ hours)
  • Prolonged recovery kinetics
  • Shrinking activity tolerance envelope
  • Progressive relapse susceptibility
Key insight:
PEM is a recovery-phase failure maintained by feedback loops, not an exertional injury or irreversible damage.
Synthesis

Synthesis Across Loop Families

Together, these five loop families explain how the SMPDL3B-shedding phenotype can:

  • persist without continuous inflammation
  • oscillate between relative stability and decompensation
  • evade detection by resting tests
  • worsen despite partial recovery
  • respond paradoxically to mistimed interventions

The defining feature is state-dependent threshold lowering across membrane, vascular, autonomic, metabolic, and immune systems, producing an oscillatory but self-reinforcing disease architecture.

One-Sentence Integration
In the SMPDL3B-shedding phenotype, interacting feedback loop families convert transient stress into delayed, cumulative system failure by lowering recovery-phase thresholds rather than by producing fixed structural damage.

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Why Post-Exertional Malaise (PEM) Is Delayed in the SMPDL3B-Shedding Phenotype

Key point:
In the SMPDL3B-shedding phenotype, PEM reflects a recovery-phase failure, not an immediate exertional injury.

Explanation

During exertion or stress, the system often appears to compensate adequately. Perfusion, autonomic tone, and metabolic output may be temporarily maintained through sympathetic activation, redistributed blood flow, and short-term buffering mechanisms.

However, the highest physiological demand occurs after the stressor has ended, during recovery, when multiple processes peak simultaneously:

  • ATP replenishment and mitochondrial repair
  • Ion rebalancing (Na⁺/Ca²⁺ homeostasis)
  • Membrane repair and lipid raft re-stabilization
  • Inflammatory resolution
  • Metabolic clearance and hepatic buffering

In the SMPDL3B-shedding phenotype, this recovery window coincides with maximum vulnerability. Delayed mitochondrial stress, calcium dysregulation, and oxidative signaling peak during recovery, re-engaging PI-PLC activity and episodic SMPDL3B shedding after exertion has ceased.

This delayed membrane instability destabilizes immune regulation, endothelial signaling, ion handling, and metabolic buffering simultaneously, producing delayed, multi-system symptom exacerbation rather than immediate collapse.

Clinical implication

PEM timing reflects when repair demand exceeds system capacity, not when effort occurs. This explains why:

  • symptoms worsen hours to days after activity
  • patients may feel “fine” immediately after exertion
  • repeated minor overexertion accumulates into severe relapse
Bottom line:
PEM is a maintenance behavior of interacting feedback loops, centered on recovery-phase vulnerability, rather than a direct marker of exertional damage.
Figure 3 — Why post-exertional malaise (PEM) is delayed in the SMPDL3B-shedding phenotype PEM timing reflects when recovery-phase repair demand exceeds system capacity, not when exertion occurs Exertion / stress phase Recovery phase (peak combined demand) start end of stressor early recovery late recovery hours–days physiological load / demand vs capacity (conceptual) repair demand system capacity stressor ends PEM window Processes peaking during recovery ATP replenishment and mitochondrial repair Ion rebalancing (Na⁺/Ca²⁺ homeostasis) Membrane repair and lipid raft re-stabilization Inflammatory resolution Metabolic clearance and hepatic buffering Key point During exertion, compensation can appear adequate. During recovery, delayed stress re-engages PI-PLC activity and episodic SMPDL3B shedding after exertion has ceased. PEM timing reflects when repair demand exceeds system capacity, not when effort occurs.
Figure 3. Why Post-Exertional Malaise (PEM) Is Delayed in the SMPDL3B-Shedding Phenotype. Key point: In the SMPDL3B-shedding phenotype, PEM reflects a recovery-phase failure, not an immediate exertional injury. During exertion or stress, the system often appears to compensate adequately. However, the highest physiological demand occurs after the stressor has ended, during recovery, when multiple processes peak simultaneously: ATP replenishment and mitochondrial repair; ion rebalancing (Na⁺/Ca²⁺ homeostasis); membrane repair and lipid raft re-stabilization; inflammatory resolution; and metabolic clearance and hepatic buffering. In this recovery window, delayed mitochondrial stress, calcium dysregulation, and oxidative signaling peak during recovery, re-engaging PI-PLC activity and episodic SMPDL3B shedding after exertion has ceased. PEM timing therefore reflects when repair demand exceeds system capacity, not when effort occurs.

What This Model Does Not Claim (Interpretation Guardrails)

To prevent misapplication or over-interpretation, the SMPDL3B-shedding feedback-loop architecture explicitly does not claim the following:

  • This model does not assume permanent structural damage
    The architecture describes functional, state-dependent instability, not irreversible tissue injury. Partial recovery between episodes is expected and observed.
  • This model does not propose continuous immune activation
    Innate signaling is primed and episodic, not constitutively elevated. Fluctuating biomarkers and normal resting tests are compatible with this framework.
  • This model does not imply that all patients express all loops
    Feedback loops are probabilistic and context-dependent. Loop dominance varies by phenotype, illness stage, stress load, and intervention timing.
  • This model does not function as a diagnostic tool
    The framework is intended for mechanistic reasoning, phenotype stratification, and hypothesis generation — not diagnosis or individual clinical decision-making.
  • This model does not claim universal causality
    SMPDL3B shedding is positioned as a state-dependent gate and amplifier, not a singular cause of ME/CFS or related conditions.

What the model does claim

  • Disease persistence can arise from threshold-lowering feedback loops without fixed pathology
  • Delayed PEM can be explained mechanistically without invoking deconditioning or psychosomatic factors
  • Recovery quality, not just activity level, is central to relapse risk
Bottom line:
This framework explains how instability is maintained — not who has the disease, how severe it must be, or how it should be treated.

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Appendix A

Canonical Framework Loops ↔ Feedback Loop Family Cross-Reference

SMPDL3B-Shedding Phenotype (v2.4)

Purpose of this table
This appendix maps the linear mechanistic loops defined in the SMPDL3B-Shedding Systems Framework v2.4 to the closed feedback loop families described in the main text. It allows readers to move bidirectionally between:

  • causal sequence (what happens)
  • persistence logic (why it keeps happening)

without re-reading the full framework.

Table A1. Framework Loop → Feedback Loop Family Mapping
Framework Loop Primary Feedback Loop Family Functional Role in Persistence Architecture
1 Family I — Priming & Trigger Readiness EV high-mannose glycome signaling maintains innate alertness and lowers downstream activation thresholds without sustained inflammation
2 Family I — Priming & Trigger Readiness ER–Golgi stress biases trafficking and proteolytic permissiveness, preparing membranes for episodic shedding rather than fixed suppression
3 Family II — Shedding Execution & Threshold Lowering Ion handling instability (Na⁺ → Ca²⁺) links transient membrane loss to stress-responsive signaling and innate sensitization
4 Family II — Shedding Execution & Threshold Lowering Lipid raft destabilization lowers TLR4 activation thresholds, enabling episodic innate hyper-responsiveness
5 Family II — Shedding Execution & Threshold Lowering PI-PLC–mediated GPI-anchor cleavage executes SMPDL3B shedding, directly reinforcing membrane instability
6 Family II — Shedding Execution & Threshold Lowering Calcium-dependent mitochondrial stress and ROS amplify ER stress and protease permissiveness, accelerating repeat shedding
7 Family III — Functional Perfusion Failure Endothelial NO signaling becomes brittle under demand due to calcium and oxidative stress, impairing adaptive vasodilation
8 Family III — Functional Perfusion Failure Perfusion distribution failure produces regional ischemia despite normal global hemodynamics, feeding back into metabolic stress
9 Family IV — Autonomic & Renal Lock-In Sympathetic compensation stabilizes perfusion short-term but increases calcium flux and demand, promoting future shedding
10 Family IV — Autonomic & Renal Lock-In State-dependent renal hypoperfusion destabilizes volume regulation, worsening orthostatic stress and autonomic drive
11 Family V — Recovery Failure & Relapse Architecture Episodic hepatic metabolic load limits recovery depth, prolonging oxidative stress and increasing re-trigger susceptibility
12 Family V — Recovery Failure & Relapse Architecture Delayed recovery-phase ATP buffer failure produces PEM timing and re-engages membrane instability after exertion
13 Family V — Recovery Failure & Relapse Architecture Incomplete immune resolution lowers innate activation thresholds, enabling repeated flares without continuous inflammation
14 Family V — Recovery Failure & Relapse Architecture Pain and sensory amplification increase autonomic load, indirectly promoting perfusion instability and renewed shedding
15 Family V — Recovery Failure & Relapse Architecture Residual instability after each crash erodes thresholds over time, producing a relapse-prone system
16 Family V — Recovery Failure & Relapse Architecture Final common pathway: load-dependent SMPDL3B shedding maintains delayed PEM as a system-level attractor
Interpretation Notes (Reviewer Guardrails)
  • Not all patients express all loops simultaneously; dominance is state- and phase-dependent.
  • Feedback loops describe probabilistic reinforcement, not inevitability.
  • Absence of abnormal resting tests does not exclude this architecture.
  • The table does not imply linear progression; loops interact bidirectionally.
  • This appendix maps mechanistic lineage, not treatment targets.

How to Use This Appendix

  • Main text: understand system behavior via loop families
  • Appendix: verify mechanistic completeness and traceability
  • Researchers: identify dominant loops for hypothesis generation
  • Trial designers: align interventions with phase-specific vulnerability

One-Line Summary (Appendix)
This cross-reference table demonstrates that persistence, delayed PEM, and relapse in the SMPDL3B-shedding phenotype emerge from interacting feedback loops distributed across membrane, vascular, autonomic, metabolic, and immune systems, rather than from a single dominant defect.


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Figure 2 — Dynamic contrast between SMPDL3B-shedding and SMPDL3B-deficient phenotypes Same downstream features, different system architecture: episodic gating vs baseline constraint Left panel SMPDL3B-Shedding Episodic, state-dependent shedding → oscillatory instability Temporal behavior primed at baseline → destabilized during stress → most vulnerable during recovery delayed PEM (recovery-phase) Mechanistic architecture Baseline priming: ER–Golgi stress + altered EV glycosylation Episodic execution: PI-PLC → SMPDL3B shedding → Na⁺/Ca²⁺ stress Downstream expression: brittle eNOS/NO → perfusion distribution failure Recovery failure: delayed stress re-engages PI-PLC → threshold erosion incomplete recovery → re-trigger Right panel SMPDL3B-Deficient Baseline membrane fragility → persistent constraint, less inter-episode reset Temporal behavior persistent baseline fragility → lower capacity for recovery between stress windows reduced inter-episode reset Mechanistic architecture Baseline constraint: chronic under-expression → membrane fragility Ion/perfusion instability more continuously expressed Downstream overlap: perfusion impairment + autonomic dysregulation Less capacity for partial reset → sustained vulnerability Shared downstream observations can arise from different architectures: episodic gating (shedding) vs baseline constraint (deficient).
Figure 2. Dynamic contrast between SMPDL3B-shedding and SMPDL3B-deficient phenotypes. Although both phenotypes share downstream features such as perfusion impairment, autonomic dysregulation, and post-exertional symptom exacerbation, their system architectures differ fundamentally. In the SMPDL3B-shedding phenotype (left), membrane instability is episodic and state-dependent, producing oscillatory behavior, delayed post-exertional malaise (PEM), and relapse driven by recovery-phase vulnerability and threshold erosion. In the SMPDL3B-deficient phenotype (right), chronic under-expression of SMPDL3B produces baseline membrane fragility, persistent ion and perfusion instability, and less capacity for inter-episode recovery. This contrast explains why similar stressors produce delayed, episodic crashes in some patients and persistent baseline dysfunction in others.

Closing Perspective

This framework is not intended to define a single cause of ME/CFS, nor to replace existing vascular, autonomic, immune, or metabolic models. Instead, it offers a systems-level explanation for how delayed post-exertional malaise, oscillatory relapse, and apparent recovery failure can emerge from interacting feedback loops without requiring fixed structural damage or continuous inflammation.

By making membrane gating, threshold dynamics, and recovery-phase vulnerability explicit, the SMPDL3B-shedding architecture reframes ME/CFS as a recovery-limited, state-dependent systems disorder. In this view, symptom exacerbation reflects when physiological demand exceeds adaptive capacity during recovery, rather than when exertion occurs.

The value of this model lies not in definitive claims, but in its ability to generate testable predictions, guide phenotype stratification, and clarify why timing, load, and recovery quality so strongly shape clinical outcomes. As new data emerge, individual loops may be revised or replaced, but the core insight—that persistence and relapse arise from interacting feedback dynamics rather than isolated defects—remains a useful organizing principle.

Framework Context & Related Documents